CASK Research

CASK gene disorders

A parent's guide to reading a genetic report

Genetic reports can look overwhelming at first. They are often written for doctors and scientists, so they contain lots of abbreviations, numbers and technical language. This guide explains some of the most common terms in plain English.

The basics

A genetic report is looking for changes (called variants or mutations) in a person's DNA.

DNA is made of four chemical "letters":

  • A = Adenine
  • T = Thymine
  • C = Cytosine
  • G = Guanine

These letters are arranged in a specific order, rather like letters in a sentence. Genes are sections of DNA that contain instructions for making proteins. Proteins help the body and brain grow and function properly. If the DNA letters change, the protein may not work correctly.

Understanding the gene name

Example: CASK gene

This tells you which gene has been affected. Each gene has a unique name, rather like a book title.

What does "variant" mean?

Example: Pathogenic variant in the CASK gene

A "variant" means there is a change in the DNA sequence. Different words describe how important the change is:

  • Benign = harmless
  • Likely benign = probably harmless
  • Variant of uncertain significance (VUS) = not enough is known about this change to determine if it would cause disease
  • Likely pathogenic = probably disease-causing
  • Pathogenic = known to cause disease

Understanding the numbers and letters

You may see something like: c.2451del

This looks frightening but is just a code explaining the DNA change found:

  • c. = coding DNA sequence
  • 2451 = the position in the gene where the change happened
  • del = deletion (a piece of DNA is missing)

So c.2451del means: "A DNA letter was deleted at position 2451 in the gene."

Missense variant example

Example: c.214G>A — a single DNA letter has changed.

  • 214 = position in the gene
  • G>A = the DNA letter G has changed to A

Duplication example

Example: c.1200_1203dup

  • 1200_1203 = the section of DNA involved
  • dup = duplication

"A small section of DNA has been accidentally copied twice."

Common abbreviations in genetic reports

Abbreviation Meaning Simple explanation
del Deletion Missing DNA letters
dup Duplication Extra copy of DNA
ins Insertion Extra DNA letters inserted
fs Frameshift The DNA message is shifted, often causing major problems
missense Missense variant One DNA letter change causes a different protein building block
nonsense Nonsense variant A change creates an early "stop signal"
splice Splice variant Affects how the gene instructions are put together

Understanding protein changes

You may also see: p.Ile818fs

The p. stands for protein. Proteins are made from smaller building blocks called amino acids.

  • Ile = the amino acid isoleucine
  • 818 = position in the protein
  • fs = frameshift

"At position 818 in the protein, the DNA change caused a frameshift." Frameshift changes often stop the protein working properly because they disrupt the rest of the genetic instructions.

Missense mutation example

Protein change: p.Arg72His

  • Arg = arginine (original amino acid)
  • 72 = position in the protein
  • His = histidine (new amino acid)

Duplication example

Protein change: p.Glu402Argfs*15

  • Glu = glutamic acid (original amino acid)
  • 402 = protein position
  • Arg = arginine (new amino acid)
  • fs = frameshift
  • *15 = a stop signal occurs 15 amino acids later

What is a frameshift?

DNA is normally read in groups of three letters:

THE CAT ATE THE RAT

If one letter is removed:

THE ATA TET HER AT…

The whole message changes. This is similar to a frameshift mutation in DNA. Frameshift variants often have a bigger effect than single-letter changes.

What does "de novo" mean?

This means the genetic change was new in the child and was not inherited from either parent. It usually happens by chance when the egg or sperm was formed. Parents did not cause this.

Common medical terms seen in CASK reports

Term Meaning
MRI A brain scan using magnets
Microcephaly Smaller than expected head size
Developmental delay Slower progress in learning or development
Cerebellar hypoplasia Part of the brain developed smaller than expected
Pontocerebellar hypoplasia (PCH) Underdevelopment of the cerebellum and pons areas of the brain

Important things to remember

  • Genetic reports are often written in technical language.
  • Two children with the same gene change can still be very different.
  • A report cannot always predict exactly how a child will develop.
  • Research into rare genetic conditions is continuing all the time.

A quick example

Deletion — Pathogenic variant in CASK gene (c.2451del p.Ile818fs)

"A disease-causing change was found in the CASK gene. One DNA letter is missing at position 2451. This changes the way the protein is read from position 818 onwards, which is likely to stop the protein working properly or being made at all."

Missense — Likely pathogenic variant in CASK gene (c.214G>A p.Arg72His)

"At position 214 in the gene, the DNA letter G changed to A. This caused the protein building block at position 72 to change from arginine to histidine. It is likely to affect the way the protein works because of an amino acid change."

Duplication — Pathogenic variant in CASK gene (c.1200_1203dup p.Glu402Argfs*15)

"A duplication changed the reading frame of the protein. From position 402 onwards, the protein instructions became altered and an early stop signal appeared shortly afterwards. This is likely to stop the protein working properly or being made at all."

Final thoughts

It is completely normal to feel overwhelmed when reading a genetic report for the first time. You do not need to understand every abbreviation immediately. Genetics teams, genetic counsellors and patient support organisations can help explain what the findings mean for your child and family.